Ectopic lacrimal gland is a rare clinical condition. Cases have been recorded in literature
describing that ectopic lacrimal tissue has been found at varying sites in and around the eye. Before
performing aesthetic blepharoplasty, however, it should be kept in mind that anomalous condition of
the lacrimal complex can lead to alterations in ocular lubrication. A 54 year-old female presented with
an aging eyelid, but accompanying no other ophthalmologic symptoms. While performing skin
incision during blepharoplasty, the right upper lid was directly exposed with prolapsed orbital lobe of
lacrimal gland, and diffuse infiltrating hyperplasia of ectopic lacrimal gland tissue in the Müller muscle
bulging out beneath the levator aponeurosis. The left upper lid also revealed ectopic lacrimal gland
tissue beneath the aponeurosis. Carefully preserving the main lacrimal complex, ectopic lacrimal
gland mass was excised. Histopathology revealed the tissue as lobules of lacrimal gland with some
dilated ducts. The ectopic lacrimal gland tissue is a rare clinical entity, and the diagnosis is rarely
made on physical bases alone. Therefore, we herein describe a unique clinical case of an ectopic
lacrimal gland generated within the Müller muscle. To our best knowledge, such a case has not yet
been described in literature